Phase I Study of Oral ONC206 for Recurrent Brain Tumors

This study is testing a new oral medication called ONC206 for adults with recurrent (returned) primary central nervous system (CNS) neoplasms, which are brain or spinal cord tumors. This includes types like glioblastoma and gliosarcoma. The main goal is to find the highest safe dose of ONC206 and understand its side effects. This is a Phase 1 study, meaning it's an early step in testing a new treatment. Researchers will be looking at how many participants experience dose-limiting toxicities (side effects that are severe enough to stop treatment) within 28 days. The study plans to enroll about 102 participants, but the current status of recruitment is unclear.

Study design
This is an open-label, dose-escalation Phase 1 study, meaning both you and the study team will know which treatment you are receiving. It plans to enroll about 102 participants to determine the maximum tolerated dose of ONC206.
What's involved
You would take oral ONC206, and the dose may be adjusted based on safety and how your body processes the drug. Safety evaluations will be conducted after 28 days of therapy.
Compensation
Not stated in the trial record.
Follow-up
The primary endpoints for safety and dose-limiting toxicities are measured at 28 days.

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NCT04541082

Phase I Study of Oral ONC206 in Recurrent and Rare Primary Central Nervous System Neoplasms

Recruiting
PHASE1Ages 18+InterventionalTreatment
Jazz Pharmaceuticals
~102 participants
Updated 2025-12-18 on ClinicalTrials.gov
What's tested:ONC206

At a glance

Recruiting sites
1 of 1 listed site is recruiting right now
RecruitingSuspended, closed, or not yet open
What they're measuring
Maximum Tolerated Dose (MTD) of single-agent, oral ONC206
Measured over 28 Days
+1 more outcome measured
Central Nervous System Neoplasms
Glioblastoma
Gliosarcoma, Adult
Anaplastic Oligodendroglioma
Anaplastic Astrocytoma
Pilocytic Astrocytoma
Oligodendroglioma
Gliomatosis Cerebri
Pleomorphic Xanthoastrocytoma
Anaplastic Pleomorphic Xanthoastrocytoma
Diffuse Midline Glioma, H3 K27M-Mutant
Ependymoma
Ependymoma, Anaplastic
Medulloblastoma
Teratoid Rhabdoid Tumor
Neuroectodermal Tumors, Primitive
Neuroectodermal Tumors
Anaplastic Meningioma
Atypical Meningioma
Choroid Plexus Neoplasms
Pineal Tumor
Diffuse Astrocytoma
Glial Tumor
1 sites across 1 states
Maryland1
Clinical Trial Disclosure & Transparency
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Eligibility criteria

Inclusion

Absolute neutrophil count (ANC) ≥1,500/mcL.
Platelets ≥100,000/mcL.
Hemoglobin ≥9.0 mg/dL without transfusion in 2 prior weeks.
Total bilirubin ≤1.5 × upper limit of normal (ULN) (patients with Gilbert's syndrome may be included with total bilirubin \>1.5 × ULN if direct bilirubin is ≤1.5 × ULN).
Aspartate aminotransferase (AST) or alanine aminotransferase (ALT) ≤2.5 × ULN.
Measured or estimated creatinine clearance (CLcr) ≥40 mL/minute for patients with creatinine levels above normal. CLcr will be calculated by the Cockcroft-Gault equation for renal function. 10. (Inclusion Criterion #10 was removed in Amendment 3) 11. Patients must provide a tumor specimen (paraffin-embedded block and/or frozen tissue) from a prior resection or biopsy available that is sufficient to perform biomarker assays, ≥15 unstained slides for immunohistochemistry (IHC) analysis must be received by the NOB by the first dose of study drug (Cycle 1, Day 1). For patients with ≥10 to \<15 slides, eligibility will be reviewed on a case-by-case basis. 12. Dependent upon dose level assignment and drug formulation (i.e., capsules versus powder in bottle \[PIB\]), patients must be able to either swallow oral capsules or swallow liquids. 13. Patients must provide study-specific informed consent prior to enrollment. No Durable Power of Attorney or Next of Kin can provide initial consent. 14. Patients must be able to tolerate a magnetic resonance imaging (MRI) study with intravenous gadolinium contrast. 15. (Inclusion Criterion #15 was removed in Amendment 6) 16. Patients must have a negative COVID-19 test within 72 hours of the first dose of study drug (Cycle 1, Day 1). Patients who had documented COVID-19 infection within 90 days of treatment but more than 20 days from infection do not need to be tested. 17. (Inclusion Criterion #17 was removed in Amendment 6)

Exclusion

Corrected QT interval (QTc) ≥470 msec on screening electrocardiogram (ECG; using the QTc by Fridericia's \[QTcF\] formula);
Angina pectoris that requires the use of anti-anginal medication;
Ventricular arrhythmias except for benign premature ventricular contractions;
Supraventricular and nodal arrhythmias requiring a pacemaker or not controlled with medication;
Conduction abnormality requiring a pacemaker;
Valvular disease with documented compromise in cardiac function; and/or
Symptomatic pericarditis. 7. Patients with a history of cardiac dysfunction including any of the following:
Myocardial infarction within the last 6 months, documented by persistent elevated cardiac enzymes or persistent regional wall abnormalities on assessment of left ventricular ejection fraction function;
History of documented congestive heart failure (New York Heart Association functional classification III-IV); and/or
Documented cardiomyopathy. 8. Patients who have had an ischemic or hemorrhagic stroke in the last 3 months. If the patient has had a recent tumor resection, cerebral ischemic or hemorrhagic changes that occur peri operatively are not an exclusion. 9. Patients with refractory epilepsy are excluded. Patients with primarily or secondarily generalized seizures in the 28 days prior to study enrollment will be excluded. Peri-operative seizures, defined as seizures occurring within the 7 days after a stereotactic biopsy, open biopsy, or surgical resection will not be an exclusion as long as the patient has had no generalized seizures starting 8 days after the surgical procedure. Patients with prior seizures must be on stable doses of 1 or 2 seizure medications for at least 14 days prior to study enrollment. 10. Patients with impairment of gastrointestinal (GI) function or GI disease that may significantly alter the absorption of ONC206 (uncontrolled nausea, vomiting, diarrhea, malabsorption syndrome, or small bowel resection). 11. Patients who have been treated with any hematopoietic colony-stimulating growth factors (CSFs) (e.g., granulocyte-CSF, granulocyte-macrophage-CSF) ≤2 weeks prior to starting study drug. Erythropoietin or darbepoetin therapy, if initiated at least 2 weeks prior to enrollment, may be continued. 12. Patients who are currently taking therapeutic doses of warfarin sodium or any other coumadin derivative anticoagulant. 13. Patients who are taking strong inhibitors or inducers of cytochrome P450 (CYP) 3A4, 2D6, 1A2, 2C9, and 2C19 within at least 14 days prior to the first dose of study drug (Cycle 1, Day 1); these medications are excluded throughout the study. 14. Women who are pregnant or breast feeding. 15. Women of child-bearing potential with a positive serum pregnancy test ≤72 hours prior to the first dose of study drug (Cycle 1, Day 1). 16. Patients who are receiving concomitant standard and/or investigational anti-cancer therapy. 17. Patients with alcohol or substance abuse which, in the opinion of the Investigator, would interfere with compliance or safety. 18. Patients with the presence of any other serious and/or unstable pre-existing medical disorder, psychiatric disorder, or other conditions that could interfere with patients' safety, obtaining informed consent or compliance to the study procedures as determined by the Investigators. 19. Women of childbearing potential, defined as all women physiologically capable of becoming pregnant, or men who do not agree to use highly effective contraception during treatment and for 16 additional weeks after the final dose of study drug.
True abstinence: When this is in line with the preferred and usual lifestyle of the patient. Periodic abstinence (e.g., calendar, ovulation, symptothermal, post-ovulation methods) and withdrawal are not acceptable methods of contraception.
Sterilization: Females must have had surgical bilateral oophorectomy (with or without hysterectomy) or tubal ligation at least 6 weeks ago. In case of oophorectomy alone, only when the reproductive status of the woman has been confirmed by follow up hormone level assessment.
Male partner sterilization (with the appropriate post-vasectomy documentation of the absence of sperm in the ejaculate). For female patients on the study, the vasectomized male partner should be the sole partner for that patient.
If patients are not practicing true abstinence and/or if the patient or sexual partner have not had a sterilization procedure as listed above, patients and their sexual partners must follow double barrier contraception in accordance with the guidelines for contraception below:
Females of childbearing potential:
Must use an intrauterine device or intrauterine system, during dosing of any study agent and for 16 weeks after final dose of study drug; or
Must use a double barrier method of contraception: use of an occlusive cap (diaphragm or cervical/vault cap) with spermicide for women combined with use of a condom by their male partners capable of conceiving offspring.
Males capable of conceiving offspring must use condoms during dosing of study agent and for an additional 16 weeks after final dose of study drug.
  • Maximum Tolerated Dose (MTD) of single-agent, oral ONC20628 Days

    MTD was determined by testing increasing doses up to 200 mg twice daily for 3 successive days a week. MTD reflects the highest dose of drug that did not cause a Dose-Limiting Toxicity (DLT) in \>33% of participants. DLTs will be assessed in the first course of each cohort (28 days), and refer to a study drug-related or possibly related event that meets 1 of the following criteria defined in the subsequent Primary Outcome Measure using the National Cancer Institute Common Terminology Criteria for Adverse Events Version 5.0 (NCI CTCAE 5.0).

  • Number of Participants who Experienced Dose-Limiting Toxicities (DLTs)28 Days

    DLTs will be assessed in the first course of each cohort (28 days), and refer to a study drug-related or possibly related event that meets 1 of the following criteria using NCI CTCAE 5.0: * Grade 3 or higher non-hematologic toxicity. * Grade 4 hematologic toxicity (ANC \<0.5 × 109/L and platelet count \<25 × 109/L). Lymphopenia is not considered a DLT. A confirmed DLT requires 2 consecutive measurements separated by 48 hours. * Grade 3 neutropenia (absolute neutrophil count \[ANC\] \<1.0 × 109/L) with elevated fever (\>101°F). A confirmed DLT requires 2 consecutive measurements. * Grade 3 thrombocytopenia with clinically significant bleeding. * Inability to receive the scheduled Cycle 2, Day 1 dose of study drug within 14 days due to study drug-related toxicity persisting from Cycle 1 or study drug-related toxicity newly encountered on Day 1 of Cycle 2.